Abstract
Background
Cloacal exstrophy (CE) is a rare congenital disease that requires multiple surgeries
for complex gastrointestinal and genitourinary anomalies. Long-term complications
are not uncommon; however, they are poorly reported. Pyosalpinx is sometimes encountered
during CE management in adolescents and young adults.
Case
A 28-year-old woman with a history of CE presented with fever, lower abdominal pain,
and vomiting and was diagnosed with left pyosalpinx. Computed tomography-guided drainage
and intravenous antibiotic administration were successful; however, she had 2 readmissions
for recurrent pyosalpinx 1 week after discharge and again 4 months later. She was
administered Dienogest, a synthetic progestin, to prevent recurrent pyosalpinx and
had no recurrence for 8 months.
Summary and Conclusion
Dienogest is a conservative treatment choice for preventing the recurrence of pyosalpinx
for patients with CE.
Key Words
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References
- Spectrum of Cloacal Exstrophy.in: Seminars in Pediatric Surgery. 20. 2011: 113-118
- Long-term active problems in patients with cloacal exstrophy: a systematic review.J Pediatr Surg. 2022; 57: 339-347
- Gynecologic concerns in patients with cloacal anomaly.Semin Pediatr Surg. 2016; 25: 90-95
- Pelvic inflammatory disease.N Engl J Med. 2015; 372: 2039-2048
- Fate of the uterus in 46XX cloacal exstrophy patients.J Pediatr Surg. 2013; 48: 2043-2046
- Tubo-ovarian abscess after colonic vaginoplasty for high cloacal anomaly in a 13-year-old girl.Eur J Pediatr Surg. 2002; 12: 345-347
- Dienogest reduces endometrioma volume and endometriosis-related pain symptoms.J Obstet Gynaecol. 2021; 41: 1246-1251
- Hormonal treatments for endometriosis: the endocrine background.Rev Endocr Metab Disord. 2022; 23: 333-355
Article info
Publication history
Published online: February 12, 2023
Accepted:
February 3,
2023
Received in revised form:
February 2,
2023
Received:
November 4,
2022
Publication stage
In Press Journal Pre-ProofIdentification
Copyright
© 2023 North American Society for Pediatric and Adolescent Gynecology. Published by Elsevier Inc. All rights reserved.
